Novel frameshift mutation in the CHD7 gene associated with CHARGE syndrome with preaxial polydactyly

We report a male patient with multiple congenital anomalies, including coloboma, Fallot tetralogy, bilateral choanal atresia, dysmorphic features (low set malformed ears, fronto-maxillary facial angle deviation, hypertelorism, retrognathism), micropenis, preaxial polydactyly and ureter stenosis. The...

Teljes leírás

Elmentve itt :
Bibliográfiai részletek
Szerzők: Surányi Andrea
Maróti Zoltán
Tálosi Gyula
Kalmár Tibor
Kaiser László
Bereczki Csaba
Pál Attila
Keresztúri Attila
Dokumentumtípus: Cikk
Megjelent: 2016
Sorozat:CLINICAL DYSMORPHOLOGY 25 No. 3
doi:10.1097/MCD.0000000000000120

mtmt:3029126
Online Access:http://publicatio.bibl.u-szeged.hu/9802
Leíró adatok
Tartalmi kivonat:We report a male patient with multiple congenital anomalies, including coloboma, Fallot tetralogy, bilateral choanal atresia, dysmorphic features (low set malformed ears, fronto-maxillary facial angle deviation, hypertelorism, retrognathism), micropenis, preaxial polydactyly and ureter stenosis. The major abnormalities had been diagnosed in prenatal period by ultrasound examination and the clinical diagnosis of CHARGE syndrome was established in postnatal periode by sequence analysis of the CHD7 coding region pointing to a novel heterozygous 4-basepair deletion in exon 3 that leads to an early stop codon and truncated CHD7 protein. Based on previous literature reports this is the first case of CHARGE syndrome with preaxial polydactyly characterized by this frameshift mutation. This case report allows further delineation of CHARGE syndrome polymorphism.
Terjedelem/Fizikai jellemzők:98-100
ISSN:0962-8827